Search results for "Wilson disease"

showing 3 items of 3 documents

Are the new genetic tools for diagnosis of Wilson disease helpful in clinical practice?

2020

Summary The diagnosis of Wilson disease is not always easy. For many patients, a combination of tests reflecting disturbed copper metabolism may be needed. Testing for ATP7B variants has become part of the routine diagnostic approach. The methods of genetic testing include analysis of the 21 coding exons and intronic flanking sequences, in which exons with recurrent variants would be prioritised depending on the mutation frequency in the local population. If sequencing the entire ATP7B gene cannot identify 2 variants and the suspicion for Wilson disease is high, after reviewing the clinical data, WES (whole-exome sequencing) or WGS (whole-genome sequencing) could be applied. A workflow base…

DiseaseReviewIndian childhood cirrhosisBioinformaticsDNA sequencingWES whole-exome sequencingPFIC progressive familial intrahepatic cholestasisInternal MedicinemedicineImmunology and AllergyMultiplex ligation-dependent probe amplificationWGS whole-genome sequencingExome sequencingGenetic testingWilson diseaseWhole genome sequencingWhole-genome sequencingHepatologymedicine.diagnostic_testMEDNIK syndromebusiness.industryCopper metabolismGastroenterologyMLPA multiplex ligation-dependent probe amplificationmedicine.diseaseICC Indian childhood cirrhosisNGS next-generation sequencingDMR differentially methylated regionsWhole-exome sequencingNext-generation sequencingbusinessICT idiopathic or primary copper toxicosisCDG congenital disorders of glycosylationGenetic diseasesJHEP Reports
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Wilson's disease in Spain: validation of sources of information used by the Rare Diseases Registries

2021

[ES] Objetivo: Evaluar las fuentes de información empleadas por los Registros Autonómicos de Enfermedades Raras (RAER) para la captación de la enfermedad de Wilson en España, calcular su prevalencia y mortalidad, y describir las características sociodemográficas de las personas afectadas. Método: Estudio epidemiológico transversal, periodo 2010-2015. Se captaron los posibles casos mediante los códigos 275.1 (CIE-9-MC), E83.0 (CIE-10) y 905 ORPHA en 15 RAER y el Registro de Pacientes de Enfermedades Raras del Instituto de Salud Carlos III. Los diagnósticos fueron validados revisando la documentación clínica. Se calcularon el valor predictivo positivo (VPP) de las fuentes de información, la p…

AdultMalemedicine.medical_specialtyHealth information systemsEpidemiologyPopulationEnfermedad de WilsonPrimary careSistemas de información en saludYoung Adult03 medical and health sciences0302 clinical medicineHepatolenticular DegenerationClinical historyPrevalencemedicineEpidemiologíaHumansRegistries030212 general & internal medicineFuentes de datoseducationWilson diseaseGynecologyeducation.field_of_study030505 public healthEnfermedades rarasbusiness.industryPublic Health Environmental and Occupational HealthHospital discharge databaseData sourcesAtencion primariaPredictive valueRare diseasesCross-Sectional StudiesSpainFemalePublic aspects of medicineRA1-1270Prevalencia0305 other medical sciencebusinessGaceta Sanitaria
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Outcomes of Liver Transplant for Adults With Wilson’s Disease

2020

Wilson's disease (WD) is a rare genetic disorder with protean manifestations. Even if liver transplantation (LT) could represent an effective therapeutic option for patients with end-stage liver disease, it has remained controversial in the presence of neuropsychiatric involvement. This study aimed to examine the frequency of adult LT for WD in Italy, focusing on the disease phenotype at the time of LT. A retrospective, observational, multicenter study was conducted across Italy exploring the frequency and characteristics of adults transplanted for WD between 2006 and 2016. A total of 29 adult WD patients underwent LT during the study period at 11 Italian LT centers (accounting for 0.4% of …

AdultMalewilson disease liver transplantationmedicine.medical_specialtymedicine.medical_treatmentwilson diseaseDisease030230 surgeryLiver transplantationSeverity of Illness IndexGastroenterologyEnd Stage Liver Disease03 medical and health sciencesLiver disease0302 clinical medicineHepatolenticular DegenerationInternal medicineAcute on chronic liver failuremedicineHumansRetrospective StudiesTransplantationHepatologybusiness.industrySettore MED/09 - MEDICINA INTERNAWilsonGenetic disorderPatient survivalmedicine.diseaseLong-term outcomeLiver TransplantationNeuropsychiatric symptomsWilson's diseaseTreatment OutcomeItalyCirrhosisMulticenter studyAcute on chronic liver failure; Cirrhosis; Long-term outcome; Neuropsychiatric symptomsFemale030211 gastroenterology & hepatologySurgerybusinessNeurological impairmentLiver Transplantation
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